journal article·2021-12-18Open access

Detection of Pitt–Hopkins Syndrome Based on Morphological Facial Features

Elena D’Amato, Constantino Carlos Reyes-Aldasoro, Arianna Consiglio, Gabriele D’Amato, Maria Felicia Faienza, Marcella Zollino

Applied Sciences· Volume 11· Issue 24

Abstract

This work describes a non-invasive, automated software framework to discriminate between individuals with a genetic disorder, Pitt–Hopkins syndrome (PTHS), and healthy individuals through the identification of morphological facial features. The input data consist of frontal facial photographs in which faces are located using histograms of oriented gradients feature descriptors. Pre-processing steps include color normalization and enhancement, scaling down, rotation, and cropping of pictures to produce a series of images of faces with consistent dimensions. Sixty-eight facial landmarks are automatically located on each face through a cascade of regression functions learnt via gradient boosting to estimate the shape from an initial approximation. The intensities of a sparse set of pixels indexed relative to this initial estimate are used to determine the landmarks. A set of carefully selected geometric features, for example, the relative width of the mouth or angle of the nose, is extracted from the landmarks. The features are used to investigate the statistical differences between the two populations of PTHS and healthy controls. The methodology was tested on 71 individuals with PTHS and 55 healthy controls. The software was able to classify individuals with an accuracy rate of 91%, while pediatricians achieved a recognition rate of 74%. Two geometric features related to the nose and mouth showed significant statistical difference between the two populations.
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Research context

OpenAlex topics: Genetics and Neurodevelopmental Disorders · Genomic variations and chromosomal abnormalities · Williams Syndrome Research

SciVX discovery tags are terminology-based. OpenAlex topics are source-provided classifications.

Affiliations

School of Mathematics, Computer Science and Engineering City, University of London, London EC1V 0HB, UK

Institute for Biomedical Technologies, National Research Council of Italy, 70126 Bari, Italy

Neonatal Intensive Care Unit, Department of Women’s and Children’s Health, ASL Bari, “Di Venere” Hospital, 70131 Bari, Italy

Paediatric Unit, Department of Biomedical Sciences and Human Oncology, University of Bari “A. Moro”, 70126 Bari, Italy

Dipartimento Universitario Scienze della Vita e Sanità Pubblica, Sezione di Medicina Genomica, Università Cattolica del Sacro Cuore, Facoltà di Medicina e Chirurgia, 00168 Rome, Italy

Medicina Genomica, Policlinico Universitario A. Gemelli, IRCSS, 00168 Rome, Italy

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